Gene therapy being used in cystic fibrosis study at UNMC/The Nebraska Medical Center

The University of Nebraska Medical Center and its hospital partner,

The Nebraska Medical Center, have been selected as one of 12 sites participating

in a study using gene therapy techniques to treat cystic fibrosis (CF),

a genetic disease affecting approximately 30,000 children and adults in

the United States.

With cystic fibrosis, a defective gene causes the body to produce abnormally

thick, sticky mucus that clogs the lungs and leads to chronic, life-threatening

lung infections. These thick secretions also obstruct the pancreas, preventing

digestive enzymes from reaching the intestines to help break down and absorb

food. The chronic lung infections are responsible for shortening the life

expectancy for CF patients to a median of approximately 33 years. In addition,

many CF patients eventually develop diabetes.

Cystic fibrosis is really a difficult disease to treat because so many

organs are affected, said John Colombo, M.D., professor and chief of the

pediatric pulmonology section in the UNMC pediatrics department and a pediatric

pulmonologist for The Nebraska Medical Center. Its a great honor for

us to participate in this study. Were excited to be able to help in the

development of a potentially major new treatment for our CF patients. It

is exciting because it is one of the first therapies actually targeted

to treat the underlying defect.

CF is caused by a defect in a single gene. The CF gene tells cells how

to make a molecule called the CFTR protein, which is needed to keep the

proper water balance in the bronchial tubes and in linings of other internal

organs so they remain wet and clean. With CF patients, the CFTR gene has

the wrong instructions and cells cant make a CFTR protein that works properly.

Without this protein, the lung airways can become blocked with mucous secretions,

which can lead to severe, recurring respiratory infections.

Gene therapy, also called gene transfer, is an experimental procedure

that is being developed to treat a variety of diseases, including CF, by

putting normal copies of genes into cells that need them. Because genes

are located inside cells, transferring new genes from the outside of a

cell to the inside of a cell requires help.

In this study, a very small and simple virus, called AAV, has been

engineered in the laboratory to contain a normal copy of the CFTR gene.

AAV is not known to make people sick.

The AAV genes are taken out of the virus and a normal copy of the CFTR

gene is put in their place. This new gene combination is then put back

inside the virus. The combination of AAV and the CFTR gene that is being

tested in the current study is called tgAAVCF.

Once the virus has infected the cells lining the bronchi (the branching

airways within the lungs), the cells own machinery makes good CFTR from

the good copies of the gene supplied by the virus and will continue to

do so for the life of the cell.

Over the next several months, UNMC and The Nebraska Medical Center hopes

to enroll about 10 patients into the study, Dr. Colombo said. The study

provides for a total enrollment of 100 patients nationally. Two patients

have already been enrolled at the medical center and have started receiving

treatments.

Participants in the study will visit the CF center at the medical center

eight times. During two of these visits, participants will receive either

tgAAVCF or a placebo.  Participants will not know during the treatment

if they are receiving the active drug or the placebo.

A nebulizer will be used to turn the drug or the placebo into an aerosol,

which participants will breathe in through their mouths. By breathing in

through their mouths, the drug or placebo will enter the airways in the

lungs. Once the drug enters the airway, it enters cells.

We are hoping that the normal copy of the CFTR gene carried by the

drug will provide the cell with the right instructions to make properly

functioning CFTR protein and thus result in more normal mucous secretions,

Dr. Colombo said.

Two patients enrolled in The Nebraska Medical Center/UNMC study are

Kate Howard, 16, of Sioux City, Iowa, and Chad Humston, 17, of Giltner,

Neb. Both participated in a news conference held at the Medical Center.

Cystic fibrosis is a disease that reminds you that its there every

day, said Lonnel Howard, Kates mother. Kate has never had one day of

normal living. We are so excited to have Kate participating in this study.

It represents hope for the future for all CF patients.

 In an earlier Phase II study of the drug, Dr. Colombo said it

was determined that the drug appeared safe and didnt cause any serious

side effects. In addition, patients realized a statistically significant

improvement in lung function at 30 days after treatment in that study.

The phase II study has now been published in the February issue of Chest,

a leading scientific journal. It served as the basis for the current study,

a Phase IIb study, which is being conducted by Targeted Genetics Corporation

of Seattle, the company that manufactures the CF drug, and the Cystic Fibrosis

Foundation.

 Gene therapy is one of the most exciting areas of scientific

research, Dr. Colombo said. It is a potential mode of therapy for any

disease with a genetic basis, so that can encompass lots of diseases, including

several forms of cancer. The use of gene therapy in CF is probably the

biggest breakthrough weve seen since the CF gene was discovered in 1989.

 Currently, UNMC and The Nebraska Medical Center are participating

in two other gene therapy studies, said Ernie Prentice, Ph.D., associate

dean for academic affairs. These studies deal with breast cancer and prostate

cancer.

We have seen a marked increase in the number of gene therapy protocols

at UNMC in the last year, Dr. Prentice said, and we anticipate that we

will continue to see an increase in gene therapy studies in the future.

 The CF gene therapy study is being administered nationally by

Childrens Hospital and Regional Medical Center in Seattle. For more information

on the study, call (402) 559-9256.